Journal of Otolaryngology and Ophthalmology of Shandong University ›› 2022, Vol. 36 ›› Issue (1): 111-115.doi: 10.6040/j.issn.1673-3770.0.2021.443

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A case of sleep disordered breathing is the first performance of Chiari deformity in young children report and literature revier

ZHENG Li1, XU Zhifei2   

  1. 1. Department of Otorhinolaryngology & Head and Neck Surgery;
    2. Department of Respiratory Medicine, Beijing Children's Hospital, Capital Medical University/National Center for Children's Health, Beijing 100045, China
  • Published:2022-02-22

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Abstract: Objective To understand the characteristics of central sleep apnea and the clinical characteristics of the disease, and to improve the understanding of Chiari malformation combined with central sleep apnea. Methods The clinical data of a patient with Chiari malformation were retrospectively analyzed, and the characteristics of Chiari malformation combined with central sleep apnea were discussed combined with literature review. Results The child confirmed the characteristics of Chiari malformation type I combined with central sleep apnea by imaging and polysomnography. Review and summarize literatures related to Chiari malformation, together with this case, a total of 32 cases(1 adult male, 4 adult female, 12 young and young male, 15 young female)were reported. In 22 patients with sleep respiratory disorders, 13 were mainly obstructive pause, 5 were mainly central pause, one was central hypoventilation, and three showed both central and obstructive forms.Except for one patient with obstructive suspension, all the other patients underwent surgical treatment. Conclusion The problem of Chiari malformation causing sleep breathing disorder cannot be ignored. Polysomnography can help to make objective evaluation and preliminary diagnosis, and offer more information on characteristics of sleep and breathing before clinical treatment decision is made.

Key words: Sleep apnea, Central, Obstructive, Chiari malformation, Polysomnography

CLC Number: 

  • R766
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